Purpose: The purpose of this paper was to report a result of early intervention for an infant with a congenital profound unilateral hearing loss in the right ear. Methods: The infant was identified as his hearing problem through newborn hearing screening test and diagnosed with unilateral hearing loss at 5 months of age. The early intervention program was applied from 9 months to 12 months of age to prompt listening and spoken language acquisition. Korean aural rehabilitation for infants and toddlers, the program was applied to the infant, focused on parent education as a mean of facilitating the child’s language acquisition. The mother and grandmother participated in the intervention. The program was carried out once per two weeks for 3 months, and each session lasted 90 minutes. The listening, speech, and language evaluations were conducted before and after applying early intervention for 3 months to check the progress on each area. Results: The infant scored within normal range across evaluations applied on both, but largely improved especially on the vocabulary and general language development screening test at the second evaluation, taken at the 12 months of age. Conclusion: The review for what should be considered for children with the unilateral hearing loss was discussed.